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Ultrasound
Diagnosis of Abdominal Wall Defects
by Beth A. Pletcher, MD, March 2000
Abdominal wall defects occur in about
1 in 2000 live births and are being diagnosed prenatally with increasing
frequency because of widespread acceptance of maternal serum AFP
screening and use of prenatal ultrasound in otherwise uncomplicated
pregnancies. The two most common defects identified are gastroschisis
and omphalocele, which each carry with them very different risks
for the co-occurrence of a genetic disorder as well as long term
prognosis.
During the 5th to 6th week of gestation,
the lateral and ventral body walls come together to form the umbilical
cord, but it is not until about the 10th week of gestation that
the bowel is completely encased in the abdominal cavity. Disruption
of the natural intestinal migration process may lead to the appearance
of an omphalocele whereas failure of closure of the lateral and
ventral walls results in a gastroschisis defect. These two developmental
anomalies must be differentiated from other midline defects such
as a severe body-stalk anomaly or cloacal extrophy. Careful sonographic
studies can differentiate between these clinical entities and provide
valuable information to the couple facing this diagnosis.
Ultrasound can be used to answer several
questions relating to this diagnosis and will assist in providing
appropriate prognostic information and directing additional diagnostic
studies. First, the presence or absence of a membrane covering the
defect can help to differentiate between an omphalocele and gastroschisis.
The former is virtually always covered by a peritoneal membrane
whereas the latter is not. Second, evaluation of the umbilical cord
location in relation to the defect is also quite valuable since
an omphalocele is located at the insertion of the cord, a gastroschisis
next to or beside the insertion of the cord and a cloacal extrophy
below the cord insertion. A body stalk anomaly (also called limb-body
wall complex), as with an omphalocele, is directly involved with
the umbilical cord insertion, but is associated with additional
severe fetal malformations. If the abdominal wall defect is found
to be located above the umbilical cord insertion, the diagnosis
of ectopia cordis must be considered. Third, identification of specific
organs extruded beyond the abdominal wall can help to differentiate
between these clinically distinct conditions and may also provide
additional prognostic data. Clearly, evisceration of the heart would
define ectopia cordis and bladder, cloacal extrophy. However, the
presence of bowel alone can be seen with either gastroschisis or
a small omphalocele. Identification of liver in the defect is seen
most often with omphalocele and body-stalk defects. The presence
of liver in an omphalocele defect might suggest that this is a large
defect and more difficult to repair surgically, but interestingly,
the smaller omphaloceles without extrusion of the liver, are more
frequently associated with chromosomal disorders. If this was indeed
the case, it would carry a much graver prognosis. Fourth, sonographic
appearance of the bowel involved in the defect may be helpful prognostically
(especially with gastroschisis) since this defect results in chronic
exposure of the intestine to amniotic fluid and may lead to bowel
wall thickening, atresia and/or infarction. For this reason, when
gastroschisis is suspected, serial ultrasounds may assist in making
decisions about timing of delivery, especially if bowel dilatation
or wall nodularity are noted late in gestation. Last, the presence
or absence of additional malformations is most helpful in providing
prognostic information for the parents. Since the greatest risk
for associated defects and/or chromosomal abnormalities is with
the finding of an omphalocele, chromosome studies should be considered
in any fetus with this finding. Over half of all fetuses with an
omphalocele will have at least one additional malformation and one
third will have an abnormal karyotype. The occurrence of severe
scoliosis with an omphalocele is practically diagnostic of a body-stalk
anomaly. Since gastroschisis is sometimes associated with amniotic
band syndrome, a sonographic survey is also useful in this clinical
setting to evaluate the fetus for possible additional related defects
such as limb amputations, orofacial clefts or cranial defects.
The prognosis for these abdominal
wall defects is quite variable with isolated gastroschisis perhaps
carrying the best overall prognosis. Improvements in diagnosis and
postnatal surgical care in recent years have seen a steady decrease
in mortality in newborns with this condition; over 90% of such infants
now survive. Survival of infants with omphaloceles depends primarily
on the presence or absence of additional defects and whether there
is an underlying cytogenetic abnormality. Associated abnormalities
include: cardiac defects, CNS malformations as well as GI and GU
anomalies. Trisomy 18 and trisomy 13 are the most common chromosomal
problems seen with fetal omphaloceles, but is also associated with
trisomy 21, triploidy and Turner syndrome. Mortality for fetuses
with omphaloceles and additional defects is rather high at 80% and
with chromosomal anomalies approaches 100%. However, with isolated
omphalocele, mortality is much lower and recent studies suggest
a mortality rate of only about 20%. Both ectopia cordis and limb-body
wall complex carry extremely poor prognoses and are generally fatal.
Cloacal extrophy is associated with a variety of anomalies involving
the GU tract, GI tract and occasionally the heart or CNS. Mortality
rates are intermediate with about 50% survival, but long term management
is frequently more complex, requiring multiple reconstructive surgeries
and in a small subset of males, sex reassignment.
Probably the best known syndrome associated
with omphaloceles is Beckwith-Wiedemann syndrome (BWS), and should
be considered in the differential diagnosis when a fetus is found
to have this anomaly. For this reason, targeted ultrasound may be
employed to assess the fetus with an omphalocele for macrosomia,
enlarged or lobulated kidneys, macroglossia or polyhydramnios which
may or may not be present. With advances in molecular diagnosis
for BWS, it may also be possible in some fetuses to confirm this
diagnosis, but neither ultrasound nor DNA-based testing are good
enough at this time to establish this diagnosis with certainty in
most cases. However, if BWS is suspected prenatally, it could provide
the parents with some useful and encouraging information, since
the prognosis for this condition is generally quite good. Making
this diagnosis may also assist the pediatrician or neonatologist
to direct care in the newborn period and beyond.
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